TY - JOUR
AU - Farschtschi, Said
AU - Mautner, Victor-Felix
AU - Pham, Mirko
AU - Nguyen, Rosa
AU - Kehrer-Sawatzki, Hildegard
AU - Hutter, Sonja
AU - Friedrich, Reinhard E
AU - Schulz, Alexander
AU - Morrison, Helen
AU - Jones, David
AU - Bendszus, Martin
AU - Bäumer, Philipp
TI - Multifocal nerve lesions and LZTR1 germline mutations in segmental schwannomatosis.
JO - Annals of neurology
VL - 80
IS - 4
SN - 0364-5134
CY - Hoboken, NJ
PB - Wiley-Blackwell
M1 - DKFZ-2017-01927
SP - 625 - 628
PY - 2016
AB - Schwannomatosis is a genetic disorder characterized by the occurrence of multiple peripheral schwannomas. Segmental schwannomatosis is diagnosed when schwannomas are restricted to 1 extremity and is thought to be caused by genetic mosaicism. We studied 5 patients with segmental schwannomatosis through microstructural magnetic resonance neurography and mutation analysis of NF2, SMARCB1, and LZTR1. In 4 of 5 patients, subtle fascicular nerve lesions were detected in clinically unaffected extremities. Two patients exhibited LZTR1 germline mutations. This appears contrary to a simple concept of genetic mosaicism and suggests more complex and heterogeneous mechanisms underlying the phenotype of segmental schwannomatosis than previously thought. Ann Neurol 2016;80:625-628.
KW - LZTR1 protein, human (NLM Chemicals)
KW - Transcription Factors (NLM Chemicals)
LB - PUB:(DE-HGF)16
C6 - pmid:27472264
DO - DOI:10.1002/ana.24753
UR - https://inrepo02.dkfz.de/record/125803
ER -