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@ARTICLE{Schweizer:128210,
author = {Y. Schweizer and Z. Meszaros and D. Jones$^*$ and C.
Koelsche$^*$ and M. Boudalil$^*$ and P. Fiesel$^*$ and D.
Schrimpf$^*$ and R. M. Piro and S. Brehmer and A. von
Deimling$^*$ and U. Kerl and M. Seiz-Rosenhagen and D.
Capper$^*$},
title = {{M}olecular {T}ransition of an {A}dult {L}ow-{G}rade
{B}rain {T}umor to an {A}typical {T}eratoid/{R}habdoid
{T}umor {O}ver a {T}ime-{C}ourse of 14 {Y}ears.},
journal = {Journal of neuropathology and experimental neurology},
volume = {76},
number = {8},
issn = {1554-6578},
address = {Oxford},
publisher = {Oxford University Press},
reportid = {DKFZ-2017-04227},
pages = {655 - 664},
year = {2017},
abstract = {Atypical teratoid/rhabdoid tumor (AT/RT) of the central
nervous system is a highly malignant, pediatric brain tumor
typically arising de novo. Inactivation of SMARCB1 is a
defining molecular event. We present here a rare case of an
adult (35 years) low-grade SMARCB1-deleted brain tumor
with transition into prototypical AT/RT over 14 years.
Molecular analysis was performed for 3 tumor presentations
including copy number analysis, DNA methylation analysis
(450k), and whole exome sequencing. We detected the
identical somatic SMARCB1 deletion at all 3 time-points. In
an unsupervised hierarchical clustering of methylation data
together with 127 reference cases comprising 9 brain tumor
classes all 3 manifestations clustered with AT/RT. Exome
sequencing revealed an increase of mutational burden over
time. The acquired mutations and additional copy number
changes did not affect known cancer genes. In conclusion, we
demonstrate molecular changes associated with histological
and clinical transition of a low-grade brain tumor to an
adult AT/RT. Our observation of a stable disease course for
nearly 10 years in a tumor with SMARCB1 loss and an
AT/RT-like DNA methylation profile indicates that caution
may be required in the diagnostic interpretation of such
findings in adult patients.},
keywords = {SMARCB1 Protein (NLM Chemicals) / SMARCB1 protein, human
(NLM Chemicals) / Phosphopyruvate Hydratase (NLM Chemicals)},
cin = {B062 / G380 / L201 / L101},
ddc = {610},
cid = {I:(DE-He78)B062-20160331 / I:(DE-He78)G380-20160331 /
I:(DE-He78)L201-20160331 / I:(DE-He78)L101-20160331},
pnm = {317 - Translational cancer research (POF3-317)},
pid = {G:(DE-HGF)POF3-317},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:28789476},
doi = {10.1093/jnen/nlx044},
url = {https://inrepo02.dkfz.de/record/128210},
}