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@ARTICLE{Ratnaparkhe:128696,
author = {M. Ratnaparkhe$^*$ and M. Hlevnjak$^*$ and T. Kolb$^*$ and
A. Jauch and K. Maass$^*$ and F. Devens$^*$ and A. Rode$^*$
and V. Hovestadt$^*$ and A. Korshunov$^*$ and A. Pastorczak
and W. Mlynarski and S. Sungalee and J. Korbel and J. Hoell
and U. Fischer and T. Milde$^*$ and C. Kramm and M. Nathrath
and K. Chrzanowska and E. Tausch and M. Takagi and T. Taga
and S. Constantini and J. Loeffen and J. Meijerink and S.
Zielen and G. Gohring and B. Schlegelberger and E. Maass and
R. Siebert and J. Kunz and A. E. Kulozik and B. Worst$^*$
and D. Jones$^*$ and S. Pfister$^*$ and M. Zapatka$^*$ and
P. Lichter$^*$ and A. Ernst$^*$},
title = {{G}enomic profiling of {A}cute lymphoblastic leukemia in
ataxia telangiectasia patients reveals tight link between
{ATM} mutations and chromothripsis.},
journal = {Leukemia},
volume = {31},
number = {10},
issn = {1476-5551},
address = {Basingstoke},
publisher = {Nature Publ. Group},
reportid = {DKFZ-2017-04711},
pages = {2048 - 2056},
year = {2017},
abstract = {Recent developments in sequencing technologies led to the
discovery of a novel form of genomic instability, termed
chromothripsis. This catastrophic genomic event, involved in
tumorigenesis, is characterized by tens to hundreds of
simultaneously acquired locally clustered rearrangements on
one chromosome. We hypothesized that leukemias developing in
individuals with Ataxia Telangiectasia, who are born with
two mutated copies of the ATM gene, an essential guardian of
genome stability, would show a higher prevalence of
chromothripsis due to the associated defect in DNA
double-strand break repair. Using whole-genome sequencing,
fluorescence in situ hybridization and RNA sequencing, we
characterized the genomic landscape of Acute Lymphoblastic
Leukemia (ALL) arising in patients with Ataxia
Telangiectasia. We detected a high frequency of
chromothriptic events in these tumors, specifically on
acrocentric chromosomes, as compared with tumors from
individuals with other types of DNA repair syndromes (27
cases total, 10 with Ataxia Telangiectasia). Our data
suggest that the genomic landscape of Ataxia Telangiectasia
ALL is clearly distinct from that of sporadic ALL.
Mechanistically, short telomeres and compromised DNA damage
response in cells of Ataxia Telangiectasia patients may be
linked with frequent chromothripsis. Furthermore, we show
that ATM loss is associated with increased chromothripsis
prevalence in additional tumor entities.},
cin = {B060 / G380 / G340 / B062 / L101},
ddc = {610},
cid = {I:(DE-He78)B060-20160331 / I:(DE-He78)G380-20160331 /
I:(DE-He78)G340-20160331 / I:(DE-He78)B062-20160331 /
I:(DE-He78)L101-20160331},
pnm = {313 - Cancer risk factors and prevention (POF3-313)},
pid = {G:(DE-HGF)POF3-313},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:28196983},
doi = {10.1038/leu.2017.55},
url = {https://inrepo02.dkfz.de/record/128696},
}