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@ARTICLE{Ramaswamy:130383,
author = {V. Ramaswamy and M. Remke$^*$ and E. Bouffet and S. Bailey
and S. C. Clifford and F. Doz and M. Kool$^*$ and C. Dufour
and G. Vassal and T. Milde$^*$ and O. Witt$^*$ and K. von
Hoff and T. Pietsch and P. A. Northcott and A. Gajjar and G.
W. Robinson and L. Padovani and N. André and M. Massimino
and B. Pizer and R. Packer and S. Rutkowski and S.
Pfister$^*$ and M. D. Taylor and S. L. Pomeroy},
title = {{R}isk stratification of childhood medulloblastoma in the
molecular era: the current consensus.},
journal = {Acta neuropathologica},
volume = {131},
number = {6},
issn = {1432-0533},
address = {Berlin},
publisher = {Springer},
reportid = {DKFZ-2017-05462},
pages = {821 - 831},
year = {2016},
abstract = {Historical risk stratification criteria for medulloblastoma
rely primarily on clinicopathological variables pertaining
to age, presence of metastases, extent of resection,
histological subtypes and in some instances individual
genetic aberrations such as MYC and MYCN amplification. In
2010, an international panel of experts established
consensus defining four main subgroups of medulloblastoma
(WNT, SHH, Group 3 and Group 4) delineated by
transcriptional profiling. This has led to the current
generation of biomarker-driven clinical trials assigning WNT
tumors to a favorable prognosis group in addition to
clinicopathological criteria including MYC and MYCN gene
amplifications. However, outcome prediction of non-WNT
subgroups is a challenge due to inconsistent survival
reports. In 2015, a consensus conference was convened in
Heidelberg with the objective to further refine the risk
stratification in the context of subgroups and agree on a
definition of risk groups of non-infant, childhood
medulloblastoma (ages 3-17). Published and unpublished data
over the past 5 years were reviewed, and a consensus was
reached regarding the level of evidence for currently
available biomarkers. The following risk groups were defined
based on current survival rates: low risk $(>90 \%$
survival), average (standard) risk $(75-90 \%$ survival),
high risk $(50-75 \%$ survival) and very high risk
$(<50 \%$ survival) disease. The WNT subgroup and
non-metastatic Group 4 tumors with whole chromosome 11 loss
or whole chromosome 17 gain were recognized as low-risk
tumors that may qualify for reduced therapy. High-risk
strata were defined as patients with metastatic SHH or Group
4 tumors, or MYCN-amplified SHH medulloblastomas. Very
high-risk patients are Group 3 with metastases or SHH with
TP53 mutation. In addition, a number of consensus points
were reached that should be standardized across future
clinical trials. Although we anticipate new data will emerge
from currently ongoing and recently completed clinical
trials, this consensus can serve as an outline for
prioritization of certain molecular subsets of tumors to
define and validate risk groups as a basis for future
clinical trials.},
keywords = {Biomarkers, Tumor (NLM Chemicals)},
cin = {B062 / G340 / L401 / L101},
ddc = {610},
cid = {I:(DE-He78)B062-20160331 / I:(DE-He78)G340-20160331 /
I:(DE-He78)L401-20160331 / I:(DE-He78)L101-20160331},
pnm = {312 - Functional and structural genomics (POF3-312)},
pid = {G:(DE-HGF)POF3-312},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:27040285},
pmc = {pmc:PMC4867119},
doi = {10.1007/s00401-016-1569-6},
url = {https://inrepo02.dkfz.de/record/130383},
}