% IMPORTANT: The following is UTF-8 encoded. This means that in the presence
% of non-ASCII characters, it will not work with BibTeX 0.99 or older.
% Instead, you should use an up-to-date BibTeX implementation like “bibtex8” or
% “biber”.
@ARTICLE{Wefers:147249,
author = {A. Wefers$^*$ and D. Stichel$^*$ and D. Schrimpf$^*$ and R.
Coras and M. Pages and A. Tauziède-Espariat and P. Varlet
and D. Schwarz and F. Söylemezoglu and U. Pohl and J.
Pimentel and J. Meyer$^*$ and E. Hewer and A. Japp and A.
Joshi and D. E. Reuss$^*$ and A. Reinhardt$^*$ and P.
Sievers$^*$ and M. B. Casalini$^*$ and A. Ebrahimi$^*$ and
K. Huang$^*$ and C. Koelsche and H. L. Low and O. Rebelo and
D. Marnoto and A. J. Becker and O. Staszewski and M.
Mittelbronn and M. Hasselblatt and J. Schittenhelm and E.
Cheesman and R. S. de Oliveira and R. G. P. Queiroz and E.
T. Valera and V. H. Hans and A. Korshunov$^*$ and A. Olar
and K. L. Ligon and S. Pfister$^*$ and Z. Jaunmuktane and S.
Brandner and R. G. Tatevossian and D. W. Ellison and T. S.
Jacques and M. Honavar and E. Aronica and M. Thom and F.
Sahm$^*$ and A. von Deimling$^*$ and D. Jones$^*$ and I.
Blumcke and D. Capper$^*$},
title = {{I}somorphic diffuse glioma is a morphologically and
molecularly distinct tumour entity with recurrent gene
fusions of {MYBL}1 or {MYB} and a benign disease course.},
journal = {Acta neuropathologica},
volume = {139},
number = {1},
issn = {1432-0533},
address = {Heidelberg},
publisher = {Springer},
reportid = {DKFZ-2019-02372},
pages = {193-209},
year = {2020},
note = {2020 Jan;139(1):193-209#EA:B300#},
abstract = {The 'isomorphic subtype of diffuse astrocytoma' was
identified histologically in 2004 as a supratentorial,
highly differentiated glioma with low cellularity, low
proliferation and focal diffuse brain infiltration. Patients
typically had seizures since childhood and all were operated
on as adults. To define the position of these lesions among
brain tumours, we histologically, molecularly and clinically
analysed 26 histologically prototypical isomorphic diffuse
gliomas. Immunohistochemically, they were GFAP-positive,
MAP2-, OLIG2- and CD34-negative, nuclear ATRX-expression was
retained and proliferation was low. All 24 cases sequenced
were IDH-wildtype. In cluster analyses of DNA methylation
data, isomorphic diffuse gliomas formed a group clearly
distinct from other glial/glio-neuronal brain tumours and
normal hemispheric tissue, most closely related to
paediatric MYB/MYBL1-altered diffuse astrocytomas and
angiocentric gliomas. Half of the isomorphic diffuse gliomas
had copy number alterations of MYBL1 or MYB (13/25, $52\%).$
Gene fusions of MYBL1 or MYB with various gene partners were
identified in 11/22 $(50\%)$ and were associated with an
increased RNA-expression of the respective MYB-family gene.
Integrating copy number alterations and available RNA
sequencing data, 20/26 $(77\%)$ of isomorphic diffuse
gliomas demonstrated MYBL1 $(54\%)$ or MYB $(23\%)$
alterations. Clinically, $89\%$ of patients were
seizure-free after surgery and all had a good outcome. In
summary, we here define a distinct benign tumour class
belonging to the family of MYB/MYBL1-altered gliomas.
Isomorphic diffuse glioma occurs both in children and
adults, has a concise morphology, frequent MYBL1 and MYB
alterations and a specific DNA methylation profile. As an
exclusively histological diagnosis may be very challenging
and as paediatric MYB/MYBL1-altered diffuse astrocytomas may
have the same gene fusions, we consider DNA methylation
profiling very helpful for their identification.},
cin = {B300 / B062 / B360 / BE01},
ddc = {610},
cid = {I:(DE-He78)B300-20160331 / I:(DE-He78)B062-20160331 /
I:(DE-He78)B360-20160331 / I:(DE-He78)BE01-20160331},
pnm = {312 - Functional and structural genomics (POF3-312)},
pid = {G:(DE-HGF)POF3-312},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:31563982},
doi = {10.1007/s00401-019-02078-w},
url = {https://inrepo02.dkfz.de/record/147249},
}