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@ARTICLE{Ecker:186390,
author = {J. Ecker$^*$ and F. Selt$^*$ and D. Sturm$^*$ and M.
Sill$^*$ and A. Korshunov$^*$ and S. Hirsch$^*$ and D.
Capper$^*$ and N. Dikow and C. Sutter and C. Müller$^*$ and
R. Sigaud$^*$ and A. Eggert and T. Simon and T. Niehues and
A. von Deimling$^*$ and K. W. Pajtler$^*$ and C. M. van
Tilburg$^*$ and D. T. W. Jones$^*$ and F. Sahm$^*$ and S. M.
Pfister$^*$ and O. Witt$^*$ and T. Milde$^*$},
title = {{M}olecular diagnostics enables detection of actionable
targets: the {P}ediatric {T}argeted {T}herapy 2.0 registry.},
journal = {European journal of cancer},
volume = {180},
issn = {0014-2964},
address = {Amsterdam [u.a.]},
publisher = {Elsevier},
reportid = {DKFZ-2022-03157},
pages = {71 - 84},
year = {2023},
note = {#EA:B310#LA:B310#},
abstract = {Precision oncology requires diagnostic accuracy and robust
detection of actionable alterations. The Pediatric Targeted
Therapy (PTT) 2.0 program aims at improving diagnostic
accuracy by addition of molecular analyses to the existing
histological diagnosis and detection of actionable
alterations for relapsed paediatric oncology patients, in
cases with limited availability of tumour
material.Paediatric patients diagnosed with relapse or
progression of a central nervous system tumour (n = 178), a
sarcoma (n = 41) or another solid tumour (n = 44) were
included. DNA methylation array, targeted gene panel
sequencing on tumour and blood (130 genes), RNA sequencing
in selected cases and a pathway-specific
immunohistochemistry (IHC) panel were performed using
limited formalin-fixed paraffin embedded tissue from any
disease episode available. The clinical impact of reported
findings was assessed by a serial questionnaire-based
follow-up.Integrated molecular diagnostics resulted in
refined or changed diagnosis in 117/263 $(44\%)$ tumours.
Actionable targets were detected in 155/263 $(59\%)$ cases.
Constitutional DNA variants with clinical relevance were
identified in 16/240 $(7\%)$ of patients, half of which were
previously unknown. Clinical follow-up showed that 26/263
$(10\%)$ of patients received mechanism-of-action based
treatment matched to the molecular findings.Next-generation
diagnostics adds robust and relevant information on
diagnosis, actionable alterations and cancer predisposition
syndromes even when tissue from the current disease episode
is limited.},
keywords = {Brain tumour (Other) / Cancer predisposition (Other) /
Constitutional DNA variant (Other) / Molecular diagnostics
(Other) / Molecular targeted therapy (Other) / Paediatric
oncology (Other) / Precision oncology (Other) / Sarcoma
(Other)},
cin = {B310 / HD01 / B360 / B062 / B300 / BE01},
ddc = {610},
cid = {I:(DE-He78)B310-20160331 / I:(DE-He78)HD01-20160331 /
I:(DE-He78)B360-20160331 / I:(DE-He78)B062-20160331 /
I:(DE-He78)B300-20160331 / I:(DE-He78)BE01-20160331},
pnm = {312 - Funktionelle und strukturelle Genomforschung
(POF4-312)},
pid = {G:(DE-HGF)POF4-312},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:36542877},
doi = {10.1016/j.ejca.2022.11.015},
url = {https://inrepo02.dkfz.de/record/186390},
}