%0 Journal Article %A Tauziède-Espariat, Arnault %A Beccaria, Kévin %A Dangouloff-Ros, Volodia %A Sievers, Philipp %A Meurgey, Alexandra %A Pissaloux, Daniel %A Appay, Romain %A Saffroy, Raphaël %A Grill, Jacques %A Mariet, Cassandra %A Bourdeaut, Franck %A Hasty, Lauren %A Métais, Alice %A Chrétien, Fabrice %A Blauwblomme, Thomas %A Puget, Stéphanie %A Boddaert, Nathalie %A Varlet, Pascale %T A comprehensive analysis of infantile central nervous system tumors to improve distinctive criteria for infant-type hemispheric glioma versus desmoplastic infantile ganglioglioma/astrocytoma. %J Brain pathology %V 33 %N 5 %@ 1015-6305 %C Oxford %I Wiley-Blackwell %M DKFZ-2023-01258 %P e13182 %D 2023 %Z 2023 Sep;33(5):e13182 %X Recent epigenomic analyses have revealed the existence of a new DNA methylation class (MC) of infant-type hemispheric glioma (IHG). Like desmoplastic infantile ganglioglioma/astrocytoma (DIG/DIA), these tumors mainly affect infants and are supratentorial. While DIG/DIA is characterized by BRAF or RAF1 alterations, IHG has been shown to have receptor tyrosine kinase (RTK) gene fusions (ALK, ROS1, NTRK1/2/3, and MET). However, in this rapidly evolving field, a more comprehensive analysis of infantile glial/glioneuronal tumors including clinical, radiological, histopathological, and molecular data is needed. Here, we retrospectively investigated data from 30 infantile glial/glioneuronal tumors, consecutively compiled from our center. They were analyzed by two experienced pediatric neuroradiologists in consensus, without former knowledge of the molecular data. We also performed a comprehensive clinical, and histopathological examination (including molecular evaluation by next-generation sequencing, RNA sequencing, and fluorescence in situ hybridization [FISH] analyses), as well as DNA methylation profiling for the samples having sufficient material available. The integrative histopathological, genetic, and epigenetic analyses, including t-distributed stochastic neighbor embedding (t-SNE) analyses segregated tumors into 10 DIG/DIA (33.3 %K DNA-methylation (Other) %K desmoplastic infantile ganglioglioma/astrocytoma (Other) %K infant-type hemispheric glioma (Other) %K infantile (Other) %F PUB:(DE-HGF)16 %9 Journal Article %$ pmid:37349135 %R 10.1111/bpa.13182 %U https://inrepo02.dkfz.de/record/277074