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@ARTICLE{Lee:287615,
author = {H. Lee$^*$ and C. M. Camuto$^*$ and C. Niehrs$^*$},
title = {{R}-{S}pondin 2 governs {X}enopus left-right body axis
formation by establishing an {FGF} signaling gradient.},
journal = {Nature Communications},
volume = {15},
number = {1},
issn = {2041-1723},
address = {[London]},
publisher = {Nature Publishing Group UK},
reportid = {DKFZ-2024-00269},
pages = {1003},
year = {2024},
note = {DKFZ-ZMBH Alliance / #EA:A050#LA:A050#},
abstract = {Establishment of the left-right (LR, sinistral, dextral)
body axis in many vertebrate embryos relies on cilia-driven
leftward fluid flow within an LR organizer (LRO). A cardinal
question is how leftward flow triggers symmetry breakage.
The chemosensation model posits that ciliary flow enriches a
signaling molecule on the left side of the LRO that promotes
sinistral cell fate. However, the nature of this
sinistralizing signal has remained elusive. In the Xenopus
LRO, we identified the stem cell growth factor R-Spondin 2
(Rspo2) as a symmetrically expressed, sinistralizing signal.
As predicted for a flow-mediated signal, Rspo2 operates
downstream of leftward flow but upstream of the
asymmetrically expressed gene dand5. Unexpectedly, in LR
patterning, Rspo2 acts as an FGF receptor antagonist: Rspo2
via its TSP1 domain binds Fgfr4 and promotes its membrane
clearance by Znrf3-mediated endocytosis. Concordantly, we
find that at flow-stage, FGF signaling is dextralizing and
forms a gradient across the LRO, high on the dextral- and
low on the sinistral side. Rspo2 gain- and loss-of function
equalize this FGF signaling gradient and sinistralize and
dextralize development, respectively. We propose that
leftward flow of Rspo2 produces an FGF signaling gradient
that governs LR-symmetry breakage.},
cin = {A050},
ddc = {500},
cid = {I:(DE-He78)A050-20160331},
pnm = {311 - Zellbiologie und Tumorbiologie (POF4-311)},
pid = {G:(DE-HGF)POF4-311},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:38307837},
doi = {10.1038/s41467-024-44951-7},
url = {https://inrepo02.dkfz.de/record/287615},
}