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@ARTICLE{Frsti:294899,
author = {A. Försti$^*$ and F. Ambrozkiewicz and M. Marciniak and J.
Lubinski and K. Hemminki$^*$},
title = {{S}earch for germline gene variants in colorectal cancer
families presenting with multiple primary colorectal
cancers.},
journal = {International journal of cancer},
volume = {156},
number = {7},
issn = {0020-7136},
address = {Bognor Regis},
publisher = {Wiley-Liss},
reportid = {DKFZ-2024-02609},
pages = {1393-1403},
year = {2025},
note = {#EA:B062# / 2025 Apr 1;156(7):1393-1403},
abstract = {A double primary colorectal cancer (CRC) in a familial
setting signals a high risk of CRC. In order to identify
novel CRC susceptibility genes, we whole-exome sequenced
germline DNA from nine persons with a double primary CRC and
a family history of CRC. The detected variants were
processed by bioinformatics filtering and prioritization,
including STRING protein-protein interaction and pathway
analysis. A total of 150 missense, 19 stop-gain, 22
frameshift and 13 canonical splice site variants fulfilled
our filtering criteria. The STRING analysis identified 20
DNA repair/cell cycle proteins as the main cluster, related
to genes CHEK2, EXO1, FAAP24, FANCI, MCPH1, POLL, PRC1,
RECQL, RECQL5, RRM2, SHCBP1, SMC2, XRCC1, in addition to
CDK18, ENDOV, ZW10 and the known mismatch repair genes.
Another STRING network included extracellular matrix genes
and TGFβ signaling genes. In the nine whole-exome sequenced
patients, eight harbored at least two candidate DNA
repair/cell cycle/TGFβ signaling gene variants. The number
of families is too small to provide evidence for individual
variants but, considering the known role of DNA repair/cell
cycle genes in CRC, the clustering of multiple deleterious
variants in the present families suggests that these,
perhaps jointly, contributed to CRC development in these
families.},
keywords = {familial colorectal cancer (Other) / germline variant
(Other) / multiple primaries (Other) / whole‐exome
sequencing (Other)},
cin = {B062 / HD01 / Z999},
ddc = {610},
cid = {I:(DE-He78)B062-20160331 / I:(DE-He78)HD01-20160331 /
I:(DE-He78)Z999-20160331},
pnm = {312 - Funktionelle und strukturelle Genomforschung
(POF4-312)},
pid = {G:(DE-HGF)POF4-312},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:39654522},
doi = {doi:10.1002/ijc.35283},
url = {https://inrepo02.dkfz.de/record/294899},
}