TY - JOUR
AU - Velz, Julia
AU - Freudenmann, Lena
AU - Medici, Gioele
AU - Dubbelaar, Marissa
AU - Mohme, Malte
AU - Ghasemi, David R
AU - Scheid, Jonas
AU - Kowalewski, Daniel J
AU - Patterson, Angelica B
AU - Zeitlberger, Anna M
AU - Lamszus, Katrin
AU - Westphal, Manfred
AU - Eyrich, Matthias
AU - Messing-Jünger, Martina
AU - Röhrig, Andreas
AU - Reinhard, Harald
AU - Beccaria, Kévin
AU - Craveiro, Rogeiro B
AU - Frey, Beat M
AU - Sill, Martin
AU - Nahnsen, Sven
AU - Gauder, Marie
AU - Kapolou, Konstantina
AU - Silginer, Manuela
AU - Weiss, Tobias
AU - Wirsching, Hans-Georg
AU - Roth, Patrick
AU - Grotzer, Michael
AU - Krayenbühl, Niklaus
AU - Bozinov, Oliver
AU - Regli, Luca
AU - Rammensee, Hans-Georg
AU - Rushing, Elisabeth J
AU - Sahm, Felix
AU - Walz, Juliane
AU - Weller, Michael
AU - Neidert, Marian C
TI - Mapping naturally presented T cell antigens in medulloblastoma based on integrative multi-omics.
JO - Nature Communications
VL - 16
IS - 1
SN - 2041-1723
CY - [London]
PB - Springer Nature
M1 - DKFZ-2025-00288
SP - 1364
PY - 2025
AB - Medulloblastoma is the most frequent malignant primary brain tumor in children. Despite recent advances in integrated genomics, the prognosis in children with high-risk medulloblastoma remains devastating, and new tumor-specific therapeutic approaches are needed. Here, we present an atlas of naturally presented T cell antigens in medulloblastoma. We map the human leukocyte antigen (HLA)-presented peptidomes of 28 tumors and perform comparative immunopeptidome profiling against an in-house benign database. Medulloblastoma is shown to be a rich source of tumor-associated antigens, naturally presented on HLA class I and II molecules. Remarkably, most tumor-associated peptides and proteins are subgroup-specific, whereas shared presentation among all subgroups of medulloblastoma (WNT, SHH, Group 3 and Group 4) is rare. Functional testing of top-ranking novel candidate antigens demonstrates the induction of peptide-specific T cell responses, supporting their potential for T cell immunotherapy. This study is an in-depth mapping of naturally presented T cell antigens in medulloblastoma. Integration of immunopeptidomics, transcriptomics, and epigenetic data leads to the identification of a large set of actionable targets that can be further used for the translation into the clinical setting by facilitating the informed design of immunotherapeutic approaches to children with medulloblastoma.
KW - Medulloblastoma: immunology
KW - Medulloblastoma: genetics
KW - Humans
KW - Cerebellar Neoplasms: immunology
KW - Cerebellar Neoplasms: genetics
KW - Antigens, Neoplasm: immunology
KW - Antigens, Neoplasm: genetics
KW - Child
KW - T-Lymphocytes: immunology
KW - Antigen Presentation: immunology
KW - Histocompatibility Antigens Class I: immunology
KW - Histocompatibility Antigens Class I: genetics
KW - Male
KW - Female
KW - Peptides: immunology
KW - HLA Antigens: genetics
KW - HLA Antigens: immunology
KW - Proteomics
KW - Immunotherapy: methods
KW - Multiomics
KW - Antigens, Neoplasm (NLM Chemicals)
KW - Histocompatibility Antigens Class I (NLM Chemicals)
KW - Peptides (NLM Chemicals)
KW - HLA Antigens (NLM Chemicals)
LB - PUB:(DE-HGF)16
C6 - pmid:39904979
DO - DOI:10.1038/s41467-025-56268-0
UR - https://inrepo02.dkfz.de/record/298571
ER -