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@ARTICLE{Sendker:301924,
author = {S. Sendker$^*$ and M. Schneider$^*$ and E. Antoniou$^*$ and
D. Neumann and N. Niktoreh$^*$ and U. Dirksen$^*$ and N. von
Neuhoff$^*$ and U. Creutzig and D. Reinhardt and K. Waack},
title = {{I}mproved outcomes and treatment guidance in pediatric
therapy-related {AML}: {AML}-{BFM} study group
recommendations.},
journal = {Blood advances},
volume = {9},
number = {11},
issn = {2473-9529},
address = {Washington, DC},
publisher = {American Society of Hematology},
reportid = {DKFZ-2025-01194},
pages = {2831 - 2841},
year = {2025},
abstract = {Therapy-related acute myeloid leukemia (AML; tAML) is one
of the most feared therapy-emergent complications. This
study aims to determine the clinical and pathological
significance and define therapeutic implications and poor
prognosticators in pediatric tAML. We analyzed a total of
119 pediatric patients (aged 2-20 years) who were centrally
diagnosed with tAML within the Acute Myeloid Leukemia
Berlin-Frankfurt-Münster (AML-BFM) study group between 1993
and 2019. Compared with de novo AML, tAML was associated
with decreased white blood count and involvement of the
central nervous system. Latency to tAML was inversely
correlated with age at primary malignancy. Patients with
tAML were more likely to have abnormal karyotypes,
overrepresenting KMT2A rearrangements, the unfavorable
cytogenetics -7/del(7q), as well as complex and monosomal
karyotypes, whereas core-binding AML was underrepresented.
The occurrence of stratification-relevant molecular genetics
was comparable with de novo AML, whereas CEBPAdm was absent
in tAML. Survival rates in tAML improved from $10\%$ ±
$6\%$ in AML-BFM 1993/1998 to $50\%$ ± $10\%$ in the
registries 2012/2017; however, this is still worse than de
novo AML. Hematopoietic stem cell transplantation (HSCT) in
no evidence of leukemia (NEL; $<5\%$ blasts) after 2
induction cycles greatly improved survival. Adverse
cytogenetics, previous ionizing radiation (>35 Gy), and
latency ≤1 year were identified as the strongest poor
prognosticators. Over the past 26 years, outcome and
survival significantly improved in pediatric tAML. Our
results suggest that HSCT in NEL after 2 induction cycles is
the most promising therapeutic approach for achieving
improved survival. Radiation, adverse cytogenetics, and
latency ≤1 year should be considered as poor
prognosticators in pediatric tAML.},
keywords = {Humans / Child / Leukemia, Myeloid, Acute: therapy /
Leukemia, Myeloid, Acute: etiology / Leukemia, Myeloid,
Acute: mortality / Leukemia, Myeloid, Acute: diagnosis /
Adolescent / Child, Preschool / Female / Male / Young Adult
/ Treatment Outcome / Prognosis / Neoplasms, Second Primary:
therapy / Neoplasms, Second Primary: mortality / Neoplasms,
Second Primary: diagnosis / Neoplasms, Second Primary:
etiology / Disease Management},
cin = {ED01},
ddc = {610},
cid = {I:(DE-He78)ED01-20160331},
pnm = {899 - ohne Topic (POF4-899)},
pid = {G:(DE-HGF)POF4-899},
typ = {PUB:(DE-HGF)16},
pubmed = {pmid:39969195},
doi = {10.1182/bloodadvances.2024014728},
url = {https://inrepo02.dkfz.de/record/301924},
}